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Aicardi syndrome

Xp22 MIM.304050

X-linked dominant disease.

Synospsis

- systemic anomalies

  • postnatal growth retardation

- craniofacial anomalies

  • scalp lipoma
  • microcephaly
  • facial asymmetry
  • cleft lip
  • cleft palate

- ocular anomalies

  • microphthalmia
  • optic nerve coloboma
  • bilateral chorioretinopathy
  • chorioretinal lacunae
  • retinal detachment
  • cataract
  • nystagmus
  • optic atrophy

- recurrent pneumonia
- hiatal hernia
- skeletal anomalies

  • absent ribs
  • extra ribs
  • fused ribs
  • bifid ribs
  • butterfly vertebrae
  • block vertebrae
  • hemivertebrae
  • spina bifida
  • scoliosis

- limb anomalies

  • proximally placed thumbs

- cerebrospinal anomalies

  • corpus callosum agenesis
  • Dandy-Walker malformation
  • Arnold-Chiari malformation
  • cavum septum pellucidum
  • choroid plexus cyst
  • delayed myelination
  • partial-total agenesis of corpus callosum
  • enlarged lateral and third ventricles
  • cortical heterotopias
  • subependymal heterotopias
  • pachygyria
  • hypoplastic cerebellar vermis
  • infantile spasms
  • profound mental retardation
  • hypotonia

- precocious puberty

- tumoral predisposition

  • hepatoblastoma
  • benign teratoma
  • embryonal carcinoma
  • metastatic angiosarcoma